International Journal of Head and Neck Surgery

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VOLUME 9 , ISSUE 3 ( July-September, 2018 ) > List of Articles


Rhinoscleroma with Rosai–Dorfman Histiocytosis: A Case Report

Anuja Santosh Kulkarni, Prabodh Karnik

Keywords : Cervical lymphadenopathy, Rhinoscleroma, Rosai–Dorfman histiocytosis

Citation Information : Kulkarni AS, Karnik P. Rhinoscleroma with Rosai–Dorfman Histiocytosis: A Case Report. Int J Head Neck Surg 2018; 9 (3):106-109.

DOI: 10.5005/jp-journals-10001-1347

License: CC BY-NC 4.0

Published Online: 01-08-2019

Copyright Statement:  Copyright © 2018; The Author(s).


Rhinoscleroma is a well-documented entity. However, rhinoscleroma associated with lymphadenopathy is a rare clinical entity. Here, we report a case of rhinoscleroma with cervical lymphadenopathy of Rosai–Dorfman histiocytosis in a 57-year-old female patient who presented to us with a history of nasal obstruction of 1-year duration and neck swelling of 2 months duration along with constitutional symptoms such as malaise.

  1. Cannady Steven B, Citardi Martin J, et al. Granulomatous Diseases of the Nose and Paranasal Sinuses. In. de-Souza C, Har-el G. ed. Head and Neck Surgery, 1st ed., Jitendar P. Vij, India: Jaypee Brothers Medical Publishers(P), Ltd.; 2009. p. 367, vol. 1, ch. 26.
  2. Rosai J, Dorfman RF. Sinus histiocytosis with massive lymphadenopathy. Arch Pathol 1969;87:63–70.
  3. Foucar E, Rosai J, et al. Sinus histiocytosis with massive lymphadenopathy (Rosai–Dorfman disease): review of the entity. Semin Diagn Pathol 1990;7(1):19–73. PMID 2180012, //
  4. Pulsoni A, Anghel G, et al. Treatment of sinus histiocytosis with massive lymphadenopathy (Rosai–Dorfman disease): report of a case and literature review. Am J Hematol 2002;69:67–71. DOI: 10.1002/ajh.10008.
  5. Cooper SL, Chavis PS, et al. A case of orbital Rosai–Dorfman disease responding to radiotherapy. J Pediatr Hematol Oncol 2008;30: 744–748. DOI: 10.1097/MPH.0b013e31817e4ac1.
  6. Oka M, Kamo T, et al. Successful treatment of Rosai-Dorfman disease with low-dose oral corticosteroid. J Dermatol 2009;36:237–240. DOI: 10.1111/j.1346-8138.2009.00630.x.
  7. Naraghi M, Madani SZ, et al. Coincidence of Rhinoscleroma and Rosai–Dorfman Disease (sinus histiocytosis with massive lymphadenopathy): report of a case. Acta Med Iran 2002;40(1):11–15.
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